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Presentación clínica y evolución del isomerismo derecho;
Clinical Presentation and Outcome of Right Isomerism

Creators:Lafuente, María Victoria; Cardióloga Infantil.
Hospital J P Garrahan, Villalba, Claudia Natalia; Cardiologa Infantil, Mouratian, Mariela Diana; Jefa de Clínica del Servicio de Cardiología del Hospital J P Garrahan, Villa, Alejandra; Jefa de Clínica del Servicio de Cardiología del Hospital J P Garrahan, Sciegata, Alberto Miguel; Jefe del Servicio de Hemodinamia, García Delucis, Pablo; Jefe a cardo del Servicio de Cirugía Cardiovascular del Hospital JP Garrahan, Capelli, Horacio; Jefe del Servicio de Cardiología del Hospital J P Garrahan

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 Objetivo:Reportar las características clínicas,conductas y resultados del dextroisomerismo en nuestra población hospitalaria. Material y métodos:Entre1997-2011se identificaron 72pacientes(p)con una mediana de seguimiento de 5.1años(rango 1-26 años) Resultados:En el 91,7%la presentación fue neonatal,66p con cianosis y6p con insuficiencia cardíaca. Las características anatómicas más frecuentes fueron:válvula AV común(N=56),obstrucción pulmonar(N=67),conexión ventrículoarterial discordante(N=44)y tipo doble salida(N=27), aurícula única(N=25),vena cava superior bilateral sin innominada(N=30),anomalía total del retorno venoso pulmonar(ARVP)(N=43),asplenia (N= 53). Se detectaron anomalías extracardíacas en11p. Al 76,38%se les indicó tratamiento quirúrgico,el estadio máximo alcanzado fue la cirugía paliativa14p,Glenn17p,bypass de ventrículo subpulmonar (BPVP)23p,1p cirugía ventrículo uno y medio. La mortalidad global fue39,45%(N=28);para los diferentes procedimientos paliativos(29%),para el estadio Glenn(29%)yBTVP(21,76%). En el análisis univariado la mortalidad asociada a ARVP infradiafragmática fue significativa p0,02.Para el estadio Glenn la mortalidad se relacionó al Glenn bilateral p0.04,mientras que para el BTVP no se identificó una causa determinada. En los estadios de la cirugía univentricular desarrollaron estenosis de venas pulmonares(3p),colaterales aortopulmonares(4p)y progresión a insuficiencia AV severa(2p). Conclusiones: En la mayoría la  edad de presentación fue neonatal y con clínica de cianosis.En el dextrosiomerismo la fisiología univentricular es predominante.Se detectaron 15%de anomalías extracardíacas.La mortalidad de los pacientes no quirúrgicos y con cirugía paliativa estuvo asociada a ARVP infradiafragmática.En el estadio de Glenn la mortalidad se relacionó con el tipo bilateral.Solamente un tercio de los pacientes pudo alcanzar el estadio de BTVP.Los eventos en el seguimiento a mediano plazo en los pacientes en estadio Glenn y BTVP son frecuentes. 

Background: Right isomerism is one of the most complex forms of congenital heart disease. Recent advances in medicaltreatment and surgical procedures have allowed addressing the management of these patients. Nevertheless, the prognosisremains uncertain or unsatisfactory.Objective: The aim of this study was to report the clinical characteristics, management and outcomes of right isomerism inour hospital population.Methods: This was a retrospective cohort design study conducted at Hospital Nacional de Pediatría “Prof. Dr. Juan P. Garrahan”.Between 1997 and 2011, 72 patients with median follow-up of 5.1 years (1 and 26 years) were identified.Results: In 91.7% of cases, patients were in the neonatal period, 66 patients with cyanosis and 6 patients with heart failure.The most frequent anatomic lesions were: common AV valve (n=56), pulmonary obstruction (n=67), ventriculoarterialdiscordance (n=44) and double outlet right ventricle (n=27), commom atrium (n=25), bilateral superior vena cava withoutinnominate vein (n=30), total anomalous pulmonary venous return (APVR) (n=43) and asplenia (n=53).Extracardiac lesions were detected in 11 patients.

Metadatos destacados

Colecciones
Argentine Journal of Cardiology

Editor

Sociedad Argentina de Cardiología

Fuente

Revista Argentina de Cardiología; Vol 83, No 5 (2015); 400-405, Argentine Journal of Cardiology; Vol 83, No 5 (2015); 400-405

Citación

Lafuente, María Victoria; Cardióloga Infantil. Hospital J P Garrahan et al., “Presentación clínica y evolución del isomerismo derecho,” Archivo PPCT, consulta 2 de abril de 2026, http://archivoppct.caicyt.gov.ar/items/show/8689.

Dublin Core

Autor

Lafuente, María Victoria; Cardióloga Infantil.
Hospital J P Garrahan
Villalba, Claudia Natalia; Cardiologa Infantil
Mouratian, Mariela Diana; Jefa de Clínica del Servicio de Cardiología del Hospital J P Garrahan
Villa, Alejandra; Jefa de Clínica del Servicio de Cardiología del Hospital J P Garrahan
Sciegata, Alberto Miguel; Jefe del Servicio de Hemodinamia
García Delucis, Pablo; Jefe a cardo del Servicio de Cirugía Cardiovascular del Hospital JP Garrahan
Capelli, Horacio; Jefe del Servicio de Cardiología del Hospital J P Garrahan

Fuente

Revista Argentina de Cardiología; Vol 83, No 5 (2015); 400-405
Argentine Journal of Cardiology; Vol 83, No 5 (2015); 400-405

Editor

Sociedad Argentina de Cardiología

Fecha

2015-11-30

Derechos

Los que firman al pié, certificamos que tenemos total responsabilidad por la conducción de este estudio y por el diseño y la interpretación de los datos. Nosotros escribimos el manuscrito y somos responsables por la decisión acerca del mismo. Cada uno de nosotros cumple la definición de autor como se afirma en el Comité Internacional de Editores de Revistas Médicas (International Committee of Medical Journal Editors, ver www.icmje.org). Nosotros hemos visto y aprobado el manuscrito final. Ni el artículo, ni ninguna parte esencial del mismo, incluido las tablas y las figuras, será publicado o admitido para arbitrar a otra parte antes de aparecer en la Revista.También notificamos haber leído la sección “conflicto de intereses”, y revelaríamos cualquiera que existiera. Dejamos constancia que si nuestro artículo se publicara en la RAC, cederíamos los derechos (copyright) a la Revista.Los documentos publicados en esta revista están bajo la licencia Creative Commons Atribución-NoComercial-Compartir-Igual 2.5 Argentina.
Those signing below certify that we have full responsibility for the conduction of this study and for the design and interpretation of the information. We wrote the manuscript and are responsible for its decision. Each of us fulfills the definition of authorship as stated by the International Committee of Medical Journal Editors ( www.icmje.org). We have signed and approved the final manuscript. Neither the manuscript, nor any essential part thereof, including tables and figures, will be published or accepted for refereeing elsewhere before being published in the Journal. We have also read the "Conflict of Interest" section and would disclose any existing. We state that if our manuscript is published in the RAC, we shall transfer the copyright to the Journal.

Idioma

eng
spa

Tipo

info:eu-repo/semantics/article
info:eu-repo/semantics/publishedVersion